Adoptive autoimmune hyperthyroidism following allogeneic stem cell transplantation from an HLA-identical sibling with Graves' disease

Bone Marrow Transplant. 1999 May;23(10):1091-2. doi: 10.1038/sj.bmt.1701760.

Abstract

Autoimmune diseases which follow allogeneic BMT from a donor who is a patient or a carrier of an autoimmune condition are considered to be a paradigm of adoptive autoimmunity. Seven cases of autoimmune thyroiditis associated with clinical hyperthyroidism have been published to date. In the case reported here a 35-year-old female patient with AML of the M2 subtype received unmanipulated PBSC from her HLA-identical sister who had therapeutically controlled Graves' disease. Antithyroid antibodies, including thyrotropin receptor (TSHR) antibodies, appeared 1 year after transplant. Clinical hyperthyroidism requiring thyrostatic medication appeared after 2 years. The biological and clinical implications of adoptive, post-transplant autoimmunity are briefly discussed.

Publication types

  • Case Reports

MeSH terms

  • Adoptive Transfer
  • Adult
  • Autoantibodies / blood
  • Autoimmune Diseases / etiology*
  • Autoimmune Diseases / immunology
  • Female
  • Graves Disease / immunology*
  • HLA Antigens
  • Hematopoietic Stem Cell Transplantation / adverse effects*
  • Humans
  • Hyperthyroidism / etiology*
  • Hyperthyroidism / immunology
  • Leukemia, Myeloid, Acute / therapy
  • Receptors, Thyrotropin / immunology
  • Tissue Donors
  • Transplantation, Homologous

Substances

  • Autoantibodies
  • HLA Antigens
  • Receptors, Thyrotropin