Deferiprone therapy in homozygous human beta-thalassemia removes erythrocyte membrane free iron and reduces KCl cotransport activity

J Lab Clin Med. 1999 Jan;133(1):64-9. doi: 10.1053/lc.1999.v133.a94241.

Abstract

Deposition of free iron is a characteristic feature of beta-thalassemia (beta-thal) red blood cells believed to play an important role in the generation of oxidative injury to the cell membrane. Increased red blood cell KCI cotransport, reduced K content, and cell dehydration are also found in beta-thal red blood cells. It is not known, however, whether deposition of free iron plays a role in these membrane transport changes. To explore this issue, we studied-both in vitro and in vivo-the effect on KCI cotransport of removing red blood cell membrane free iron from beta-thal erythrocytes. Eleven patients with beta-thal major who underwent long-term transfusion and were treated with deferiprone (75 mg/kg/day) for 9 months participated in the study. Deferiprone therapy removed membrane free iron from beta-thal erythrocytes, which was followed by reduced KCI cotransport activity. The reduced KCI cotransport activity was accompanied by an increase in the red blood cell K content. These data suggest that the increased activity of KCI cotransport in beta-thal red blood cells is mediated by the deposition of membrane free iron, a mechanism that may be attenuated by deferiprone therapy.

Publication types

  • Clinical Trial
  • Research Support, Non-U.S. Gov't
  • Research Support, U.S. Gov't, P.H.S.

MeSH terms

  • Adolescent
  • Adult
  • Carrier Proteins / metabolism*
  • Child
  • Chlorides / metabolism
  • Deferiprone
  • Erythrocyte Membrane / drug effects*
  • Erythrocyte Membrane / metabolism
  • Humans
  • Iron / metabolism*
  • Iron Chelating Agents / therapeutic use*
  • Potassium / metabolism
  • Pyridones / therapeutic use*
  • Sodium-Potassium-Chloride Symporters
  • beta-Thalassemia / drug therapy*
  • beta-Thalassemia / metabolism

Substances

  • Carrier Proteins
  • Chlorides
  • Iron Chelating Agents
  • Pyridones
  • Sodium-Potassium-Chloride Symporters
  • Deferiprone
  • Iron
  • Potassium