Late Epstein-Barr virus infection of a hepatosplenic gamma delta T-cell lymphoma arising in a kidney transplant recipient

Haematologica. 2000 Mar;85(3):256-62.

Abstract

Background and objective: gd T-cell lymphomas are only exceptionally observed in transplanted patients. Aim of this study was the detailed characterization of one such case.

Design and methods: The patient developed spontaneous splenic rupture six years after kidney transplantation. The splenic red pulp was infiltrated by medium-sized and large lymphoid cells with two or more nucleoli. At autopsy, similar lymphoid cells infiltrated the hepatic sinusoids. Histologic, immunologic and molecular studies were carried out.

Results: By immunohistochemistry, the atypical lymphoid cells were found to express CD3, CD45 and CD43, indicating their T-lineage origin. Approximately 99% of spleen mononuclear cells (MNC) were CD3(+), gammadelta TcR+, CD4-, CD8-, alphabeta TcR-. A clonal gammadelta TcR rearrangement (Vgamma1-Jgamma1.3/2.3-Cgamma2; Vdelta1-Ddelta2-Jdelta1) was detected. The final diagnosis was peripheral T-cell lymphoma, hepato-splenic gammadelta-type. EBV infection of spleen MNC was documented by molecular studies. However, in situ hybridization for EBER-1 (EBV-RNA) showed that only a minority of malignant lymphoid cells (5-7%) were EBV-infected.

Interpretation and conclusions: It is concluded that EBV infection was as a late event involving an already transformed gd T-cell clone.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Antigens, CD*
  • CD3 Complex / blood*
  • Cell Lineage
  • DNA, Viral / blood
  • Epstein-Barr Virus Infections / blood*
  • Epstein-Barr Virus Infections / genetics
  • Gene Rearrangement, delta-Chain T-Cell Antigen Receptor / genetics
  • Humans
  • Kidney Transplantation / immunology*
  • Leukocyte Common Antigens / blood
  • Leukosialin
  • Liver Neoplasms / immunology
  • Liver Neoplasms / pathology*
  • Liver Neoplasms / virology
  • Lymphoma, T-Cell / classification*
  • Lymphoma, T-Cell / immunology*
  • Lymphoma, T-Cell / virology
  • Male
  • Receptors, Antigen, T-Cell, gamma-delta / blood
  • Sialoglycoproteins / blood
  • Splenic Neoplasms / immunology
  • Splenic Neoplasms / pathology*
  • Splenic Neoplasms / virology

Substances

  • Antigens, CD
  • CD3 Complex
  • DNA, Viral
  • Leukosialin
  • Receptors, Antigen, T-Cell, gamma-delta
  • SPN protein, human
  • Sialoglycoproteins
  • Leukocyte Common Antigens