[Sjögren-Larsson syndrome]

Hautarzt. 2000 Apr;51(4):250-5. doi: 10.1007/s001050051113.
[Article in German]

Abstract

This rare, ubiquitous neurocutaneous disorder is inherited in an autosomal recessive fashion. Its primary clinical manifestations are congenital ichthyosis, spastic diplegia or tetraplegia, and mental retardation. The causative biochemical defect has been identified as a deficiency of the enzyme fatty aldehyde dehydrogenase, a component of fatty alcohol:NAD+ oxidoreductase. We present a case report of an affected 3.5 year old white girl to give an overview of the pre- and postnatal diagnostic procedures as well as of therapeutic options.

Publication types

  • Case Reports
  • English Abstract

MeSH terms

  • Aldehyde Oxidoreductases / deficiency
  • Aldehyde Oxidoreductases / genetics
  • Child, Preschool
  • Chromosome Aberrations / genetics
  • Chromosome Disorders
  • Female
  • Genes, Recessive / genetics
  • Humans
  • Intellectual Disability / diagnosis
  • Intellectual Disability / genetics
  • Karyotyping
  • Sjogren-Larsson Syndrome / diagnosis
  • Sjogren-Larsson Syndrome / genetics*

Substances

  • Aldehyde Oxidoreductases
  • long-chain-aldehyde dehydrogenase