Mutagenesis and carcinogenesis in nucleotide excision repair-deficient XPA knock out mice

Mutat Res. 2000 May 30;450(1-2):167-80. doi: 10.1016/s0027-5107(00)00023-3.

Abstract

Mice with a defect in the xeroderma pigmentosum group A (XPA) gene have a complete deficiency in nucleotide excision repair (NER). As such, these mice mimic the human XP phenotype in that they have a >1000-fold higher risk of developing UV-induced skin cancer. Besides being UV-sensitive, XPA(-/-) mice also develop internal tumors when they are exposed to chemical carcinogens. To investigate the effect of a total NER deficiency on the induction of gene mutations and tumor development, we crossed XPA(-/-) mice with transgenic lacZ/pUR288 mutation-indicator mice. The mice were treated with various agents and chemicals like UV-B, benzo[a]pyrene and 2-aceto-amino-fluorene. Gene mutation induction in several tumor target- and non-target tissues was determined in both the bacterial lacZ reporter gene and in the endogenous Hprt gene. Furthermore, alterations in the p53- and ras genes were determined in UV-induced skin tumors of XPA(-/-) mice. In this work, we review these results and discuss the applicability and reliability of enhanced gene mutant frequencies as early indicators of tumorigenesis.

Publication types

  • Research Support, Non-U.S. Gov't
  • Research Support, U.S. Gov't, P.H.S.

MeSH terms

  • 2-Acetylaminofluorene / toxicity
  • Animals
  • Base Sequence
  • Benzo(a)pyrene / toxicity
  • Cocarcinogenesis*
  • DNA Repair / genetics*
  • DNA, Neoplasm / genetics
  • DNA-Binding Proteins / genetics*
  • Humans
  • Hypoxanthine Phosphoribosyltransferase / genetics
  • Lac Operon
  • Mice
  • Mice, Knockout
  • Mice, Transgenic
  • Models, Genetic
  • Mutagenesis*
  • Neoplasms, Radiation-Induced / etiology
  • Neoplasms, Radiation-Induced / genetics
  • Neoplasms, Radiation-Induced / metabolism
  • RNA-Binding Proteins / genetics*
  • Skin Neoplasms / etiology
  • Skin Neoplasms / genetics
  • Skin Neoplasms / metabolism
  • Ultraviolet Rays / adverse effects
  • Xeroderma Pigmentosum / genetics
  • Xeroderma Pigmentosum / metabolism
  • Xeroderma Pigmentosum Group A Protein

Substances

  • DNA, Neoplasm
  • DNA-Binding Proteins
  • RNA-Binding Proteins
  • XPA protein, human
  • Xeroderma Pigmentosum Group A Protein
  • Xpa protein, mouse
  • Benzo(a)pyrene
  • 2-Acetylaminofluorene
  • Hypoxanthine Phosphoribosyltransferase