Evidence for a founder effect in Sicilian patients with glycogen storage disease type II

Hum Hered. 2000 Nov-Dec;50(6):331-3. doi: 10.1159/000022938.

Abstract

Glycogen storage disease type II (GSD II) is an autosomal recessive inherited disorder due to the deficiency of the enzyme acid alpha-glucosidase, which causes an accumulation of glycogen in lysosomes. The deletion of exon 18 (delta 18) is a frequent mutation associated with a severe phenotype. We analyzed 25 Italian patients, 5 of whom were found to be delta 18 carriers. All these 5 patients came from Catania, a town in Sicily. We report on the analysis of 5 intragenic single-point polymorphic markers in the delta 18 patients and on the subsequent characterization of a delta 18-associated haplotype. The frequency of this haplotype in GSD II patients and normal individuals was 1 and 0.196, respectively (chi(2) = 20.9; p < 0.001). The high frequency of the delta 18 allele in this Italian subpopulation is likely to be due to a founder effect.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Child
  • Founder Effect*
  • Gene Frequency
  • Glycogen Storage Disease Type II / genetics*
  • Haplotypes
  • Humans
  • Infant
  • Mutation
  • Polymorphism, Single Nucleotide
  • Sicily
  • alpha-Glucosidases / genetics

Substances

  • alpha-Glucosidases

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