Defective surface expression of attractin on T cells in patients with common variable immunodeficiency (CVID)

Clin Exp Immunol. 2001 Jan;123(1):99-104. doi: 10.1046/j.1365-2249.2001.01413.x.

Abstract

The proliferative responses of T lymphocytes of a subset of patients with CVID are abnormally low. This may be due to abnormalities in extracellular interactions or signalling defects downstream from membrane-associated receptors. Demonstrating that the T cell receptor signalling was normal, we observed no abnormal pattern of activation-induced tyrosine phosphorylation in cells from CVID patients. Moreover, the addition of exogenous IL-2 increased the low proliferation to mitogens, thus indicating the integrity of the IL-2R signalling apparatus. Attractin is a rapidly expressed T cell activation antigen involved in forming an association between T cells and monocytes. Twenty-four to 48 h after activation by CD3 cross-linking, attractin expression was not up-regulated on the cells of CVID patients despite normal up-regulation of CD25 and CD26. On control cells, however, attractin expression was up-regulated together with CD25 and CD26. The addition of the purified 175-kD attractin was capable of restoring the proliferative response of peripheral blood mononuclear cells following CD3 X-L in the presence of suboptimal concentrations of rIL-2 (10 and 20 U/ml). The effect was dose-dependent with the maximal effect at a concentration of 500 ng/ml, and present at a concentration as low as 50 ng/ml. Due to the likely role of attractin in cell guidance and amplification of the immune response, our results indicate that the lack of up-regulation of the molecule in patients with CVID may in turn affect any further step of productive immune response. Our finding may also imply a potential therapeutic role for this novel molecule.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Adult
  • Antigens, CD19 / biosynthesis
  • Biomarkers
  • CD3 Complex / biosynthesis
  • CD4 Antigens / biosynthesis
  • CD8 Antigens / biosynthesis
  • Cell Membrane / immunology
  • Cell Membrane / metabolism
  • Child
  • Common Variable Immunodeficiency / immunology
  • Common Variable Immunodeficiency / metabolism*
  • Dipeptidyl Peptidase 4 / biosynthesis
  • Female
  • Glycoproteins / biosynthesis*
  • Glycoproteins / deficiency*
  • Glycoproteins / physiology
  • Humans
  • Immunophenotyping
  • Interleukin-2 / pharmacology
  • Lymphocyte Activation
  • Male
  • Receptors, Interleukin-2 / biosynthesis
  • Signal Transduction / immunology
  • T-Lymphocyte Subsets / immunology*
  • T-Lymphocyte Subsets / metabolism*
  • T-Lymphocyte Subsets / pathology

Substances

  • Antigens, CD19
  • Biomarkers
  • CD3 Complex
  • CD4 Antigens
  • CD8 Antigens
  • Glycoproteins
  • Interleukin-2
  • Receptors, Interleukin-2
  • Dipeptidyl Peptidase 4

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