Requirement for presenilin 1 in facilitating lagged 2-mediated endoproteolysis and signaling of notch 1

J Mol Neurosci. 2000 Dec;15(3):189-204. doi: 10.1385/jmn:15:3:189.

Abstract

Presenilin 1 (PS1), a polytopic membrane protein, is required for endoproteolytic processing at gamma-secretase site within the transmembrane domain of amyloid precursor proteins (APP). In addition, PS1 and its orthologues facilitate signaling of Notch family members, cell-surface receptors that specify cell fates during development. To clarify the mechanism(s) by which PS facilitates Notch signaling, we examined human Jagged-2-dependent metabolism and activity of a chimeric full-length Notchl-GFP molecule expressed in fibroblasts with heterozygous, or homozygous deletions of PS1. We demonstrate that PS1 is required for facilitating Jagged 2-mediated proteolysis and that translocation and accumulation of NICD in the nucleus correlates with signaling activity. Moreover, in a ligand-independent, Ca2+-depletion paradigm, we demonstrate that PS1 facilitates endoproteolysis of a plasma-membrane-associated, Notch1-GFP derivative. Finally, we report that NICD production is inhibited by L-685,458, a potent and selective inhibitor that blocks solubilized gamma-secretase activity and Abeta production in cultured cells. These findings strongly suggest that intramembranous processing of APP and Notch 1 are mediated by similar, if not identical, proteases that require PS1 for their activation.

Publication types

  • Research Support, U.S. Gov't, P.H.S.

MeSH terms

  • Alzheimer Disease / genetics*
  • Alzheimer Disease / metabolism
  • Alzheimer Disease / physiopathology
  • Amyloid Precursor Protein Secretases
  • Amyloid beta-Protein Precursor / metabolism
  • Animals
  • Aspartic Acid Endopeptidases
  • Carbamates
  • Carrier Proteins / genetics
  • Carrier Proteins / metabolism*
  • Cell Line, Transformed / cytology
  • Cell Line, Transformed / metabolism
  • Cell Membrane / genetics
  • Cell Membrane / metabolism*
  • Cell Nucleus / genetics
  • Cell Nucleus / metabolism
  • Dipeptides
  • Endopeptidases / drug effects
  • Endopeptidases / metabolism
  • Fetus
  • Fibroblasts / cytology
  • Fibroblasts / metabolism
  • Green Fluorescent Proteins
  • Indicators and Reagents / metabolism
  • Intercellular Signaling Peptides and Proteins
  • Jagged-2 Protein
  • Luminescent Proteins / metabolism
  • Membrane Proteins / genetics
  • Membrane Proteins / metabolism*
  • Mice
  • Mice, Knockout
  • Peptide Fragments / genetics
  • Peptide Fragments / metabolism
  • Peptide Hydrolases / genetics
  • Peptide Hydrolases / metabolism*
  • Presenilin-1
  • Protease Inhibitors / pharmacology
  • Receptor, Notch1
  • Receptors, Cell Surface*
  • Recombinant Fusion Proteins / genetics
  • Recombinant Fusion Proteins / metabolism
  • Signal Transduction / genetics*
  • Transcription Factors*
  • Translocation, Genetic / genetics

Substances

  • Amyloid beta-Protein Precursor
  • Carbamates
  • Carrier Proteins
  • Dipeptides
  • Indicators and Reagents
  • Intercellular Signaling Peptides and Proteins
  • JAG2 protein, human
  • Jag2 protein, mouse
  • Jagged-2 Protein
  • L 685458
  • Luminescent Proteins
  • Membrane Proteins
  • Notch1 protein, mouse
  • PSEN1 protein, human
  • Peptide Fragments
  • Presenilin-1
  • Protease Inhibitors
  • Receptor, Notch1
  • Receptors, Cell Surface
  • Recombinant Fusion Proteins
  • Transcription Factors
  • Green Fluorescent Proteins
  • Amyloid Precursor Protein Secretases
  • Endopeptidases
  • Peptide Hydrolases
  • Aspartic Acid Endopeptidases
  • BACE1 protein, human
  • Bace1 protein, mouse