Phenotype and genotype heterogeneity in Mediterranean citrullinemia

Mol Genet Metab. 2001 Nov;74(3):396-8. doi: 10.1006/mgme.2001.3221.

Abstract

We summarize the diagnosis, outcome, and molecular studies of five Mediterranean patients with citrullinemia: four neonatal classical forms and one subacute form, who also suffers from Down syndrome and presented with severe hepatic encephalopathy at age 7. Mutational analysis revealed three alleles with a common mutation and five new mutations: two Moroccan siblings are homozygous for G390R, the subacute form is compound heterozygous for G390R/G117D (new mutation), and the two other neonatal forms are compound heterozygous for four new mutations: V69A/E270Q and T119I(R108L)/?.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Argininosuccinate Synthase / deficiency
  • Argininosuccinate Synthase / genetics*
  • Child
  • Citrullinemia / enzymology
  • Citrullinemia / genetics*
  • Citrullinemia / pathology
  • DNA / chemistry
  • DNA / genetics
  • DNA Mutational Analysis
  • DNA, Complementary / chemistry
  • DNA, Complementary / genetics
  • Genetic Heterogeneity
  • Genotype
  • Humans
  • Infant, Newborn
  • Mediterranean Region
  • Mutation
  • Phenotype

Substances

  • DNA, Complementary
  • DNA
  • Argininosuccinate Synthase