Objective: To present a case of Marfan syndrome and concurrent congenital obstructive azoospermia.
Design: Case report.
Setting: Tertiary-care academic hospital.
Patient(s): A man with Marfan syndrome and obstructive azoospermia.
Intervention(s): The patient was evaluated for azoospermia that was proved to be due to congenital absence of large segments of vas deferens and epididymis bilaterally.
Main outcome measure(s): Evaluation for testicular sperm extraction and ICSI procedure.
Result(s): The patient is a candidate for testicular sperm extraction and ICSI.
Conclusion(s): The Marfan syndrome and azoospermia may be associated in sporadic cases.