Medulloblastoma in a child with Rubenstein-Taybi Syndrome: case report and review of the literature

Pediatr Neurosurg. 2001 Nov;35(5):235-8. doi: 10.1159/000050428.

Abstract

Although medulloblastoma is usually sporadic, there are a number of uncommon predisposing germline mutation syndromes, including: Gorlin's Syndrome, Turcot's Syndrome and Li-Fraumeni Syndrome. Patients with Rubenstein-Taybi Syndrome secondary to mutation/deletion of the CBP gene on chromosome 16 are predisposed to a variety of developmental anomalies as well as cancer. We report a child with Rubenstein-Taybi syndrome who developed a cerebellar medulloblastoma and review the literature on Rubenstein-Taybi Syndrome and pediatric medulloblastoma. As the product of the CBP gene functions in a variety of signaling pathways, we discuss the molecular implications of findings a medulloblastoma in a child with Rubenstein-Taybi Syndrome.

Publication types

  • Case Reports

MeSH terms

  • Abnormalities, Multiple / genetics*
  • Abnormalities, Multiple / pathology
  • Abnormalities, Multiple / surgery
  • Cell Division / physiology
  • Cerebellar Neoplasms / genetics*
  • Cerebellar Neoplasms / pathology
  • Cerebellar Neoplasms / surgery
  • Cerebellum / pathology
  • Cerebellum / surgery
  • Humans
  • Infant
  • Intellectual Disability / genetics*
  • Intellectual Disability / pathology
  • Intellectual Disability / surgery
  • Magnetic Resonance Imaging
  • Male
  • Medulloblastoma / genetics*
  • Medulloblastoma / pathology
  • Medulloblastoma / surgery
  • Syndrome
  • Tomography, X-Ray Computed