FISH characterisation of dynamic mosaicism involving an inv dup(15) in a patient with mental retardation

Am J Med Genet. 2001 Nov 1;103(4):289-94.

Abstract

We report on a man with mental retardation and a complex karyotype with cells containing up to three morphologically distinct supernumerary marker chromosomes (SMCs) in most metaphases. Fluorescence in situ hybridisation studies using chromosome 15-specific probes characterised the presence of seven SMCs all derived from chromosome 15. The results suggest that the patient originally had a large inv dup(15) containing two copies of the Prader-Willi/Angelman critical region which became mitotically unstable, and by a process of dynamic mosaicism various morphologically distinct SMCs arose.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Angelman Syndrome / diagnosis
  • Angelman Syndrome / genetics*
  • Chromosome Aberrations
  • Chromosome Inversion
  • Chromosomes, Human, Pair 15 / genetics*
  • DNA Probes / genetics
  • Female
  • Humans
  • In Situ Hybridization, Fluorescence
  • Karyotyping
  • Lymphocytes
  • Male
  • Mosaicism / diagnosis
  • Mosaicism / genetics*
  • Prader-Willi Syndrome / diagnosis
  • Prader-Willi Syndrome / genetics*

Substances

  • DNA Probes