Persistent developmental delay despite successful bone marrow transplantation for purine nucleoside phosphorylase deficiency

J Pediatr Hematol Oncol. 2002 Jan;24(1):69-71. doi: 10.1097/00043426-200201000-00018.

Abstract

A 10-month-old girl with a history of recurrent candidiasis, developmental delay, and a fulminant varicella infection is described. The diagnosis of purine nucleoside phosphorylase (PNP) deficiency was suggested by a reduced level of serum uric acid and confirmed by measurement of PNP activity. A human leukocyte antigen-matched bone marrow transplantation resulted in immune reconstitution, but poor neurodevelopmental progression.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Alternative Splicing
  • Amino Acid Substitution
  • Bone Marrow Transplantation*
  • Chromosome Aberrations
  • Developmental Disabilities / genetics
  • Developmental Disabilities / immunology
  • Developmental Disabilities / physiopathology*
  • Disease Progression
  • Exons
  • Female
  • Humans
  • Infant
  • Lymphocyte Activation
  • Lymphocyte Count
  • Mutation, Missense
  • Purine-Nucleoside Phosphorylase / deficiency*
  • Purine-Pyrimidine Metabolism, Inborn Errors / genetics
  • Purine-Pyrimidine Metabolism, Inborn Errors / immunology
  • Purine-Pyrimidine Metabolism, Inborn Errors / therapy*
  • Sequence Deletion
  • Time Factors
  • Treatment Outcome
  • Uric Acid / blood

Substances

  • Uric Acid
  • Purine-Nucleoside Phosphorylase