Further clinical and sensorial delineation of Schinzel-Giedion syndrome: report of two cases

Am J Med Genet. 2002 May 1;109(3):211-7. doi: 10.1002/ajmg.10348.

Abstract

Schinzel-Giedion syndrome is a rare multiple congenital malformation syndrome defined by an evocative midfacial retraction, kidney and urinary malformations and multiple skeletal abnormalities associated to a recently described neurodegenerative process. Two children with SGS are reported with identical clinical findings: megacalycosis, progressive neurodegeneration with infantile spasms and hypsarrhymtic activity. Ocular investigations revealed alacrimia and corneal hypoesthesia. Computed tomography of the temporal bone showed a tuning-fork malformation of the stapes for both children. These features may contribute to further delineation of SGS as additional clinical criteria.

Publication types

  • Case Reports
  • Review

MeSH terms

  • Abnormalities, Multiple / genetics
  • Abnormalities, Multiple / pathology*
  • Child, Preschool
  • Craniofacial Abnormalities / pathology*
  • Electroencephalography
  • Electroretinography
  • Evoked Potentials, Auditory / physiology
  • Eye Diseases / pathology*
  • Eye Diseases / physiopathology
  • Heart Defects, Congenital / pathology*
  • Humans
  • Hydronephrosis / pathology
  • Infant
  • Intellectual Disability / pathology*
  • Karyotyping
  • Male
  • Stapes / abnormalities*
  • Stapes / physiopathology
  • Syndrome