Multi-institutional use of defibrotide in 88 patients after stem cell transplantation with severe veno-occlusive disease and multisystem organ failure: response without significant toxicity in a high-risk population and factors predictive of outcome

Blood. 2002 Dec 15;100(13):4337-43. doi: 10.1182/blood-2002-04-1216. Epub 2002 Aug 1.

Abstract

Veno-occlusive disease (VOD) is the most common regimen-related toxicity accompanying stem cell transplantation (SCT). Severe VOD complicated by multisystem organ failure (MOF) remains almost uniformly fatal. Preliminary experience with defibrotide (DF), a single-stranded polydeoxyribonucleotide with fibrinolytic, antithrombotic, and anti-ischemic properties, in the treatment for severe VOD has suggested safety and activity. Eighty-eight patients who developed severe VOD after SCT were treated with DF under a defined treatment plan. At diagnosis, median bilirubin was 76.95 microM (4.5 mg/dL), median weight gain was 7%, ascites was present in 84%, and abnormal hepatic portal venous flow was present in 35%. At DF initiation, median bilirubin had increased to 215.46 microM (12.6 mg/dL), and MOF was present in 97%. DF was administered intravenously in doses ranging from 5 to 60 mg/kg per day for a median of 15 days. No severe hemorrhage or other serious toxicity related to DF was reported. Complete resolution of VOD was seen in 36%, with 35% survival at day +100. Predictors of survival included younger age, autologous SCT, and abnormal portal flow, whereas busulfan-based conditioning and encephalopathy predicted worse outcome. Decreases in mean creatinine and plasminogen activator inhibitor 1(PAI-1) levels during DF therapy predicted better survival. The complete response rate, survival to day +100, and absence of significant DF-associated toxicity in this largest patient cohort reported to date confirm the results of earlier studies. Certain features associated with successful outcome may correlate with DF-related treatment effects, and prospective evaluation of DF therapy for severe VOD should allow better definition of predictors of response or failure.

Publication types

  • Clinical Trial
  • Multicenter Study

MeSH terms

  • Adolescent
  • Adult
  • Ascites / etiology
  • Ascites / mortality
  • Bilirubin / blood
  • Biopsy
  • Child
  • Child, Preschool
  • Female
  • Fibrinolytic Agents / administration & dosage
  • Fibrinolytic Agents / adverse effects
  • Fibrinolytic Agents / therapeutic use*
  • Graft vs Host Disease / complications
  • Hepatic Veno-Occlusive Disease / blood
  • Hepatic Veno-Occlusive Disease / complications
  • Hepatic Veno-Occlusive Disease / drug therapy*
  • Humans
  • Infant
  • Infusions, Intravenous
  • Liver / pathology
  • Male
  • Middle Aged
  • Multiple Organ Failure / etiology
  • Neoplasms / complications
  • Neoplasms / therapy
  • Peripheral Blood Stem Cell Transplantation / adverse effects*
  • Polydeoxyribonucleotides / administration & dosage
  • Polydeoxyribonucleotides / adverse effects
  • Polydeoxyribonucleotides / therapeutic use*
  • Prospective Studies
  • Transplantation Conditioning / adverse effects
  • Treatment Outcome

Substances

  • Fibrinolytic Agents
  • Polydeoxyribonucleotides
  • defibrotide
  • Bilirubin