Focal and segmental primary dystonia in north-western Germany--a clinico-genetic study

Acta Neurol Scand. 2003 Mar;107(3):228-32. doi: 10.1034/j.1600-0404.2003.01362.x.

Abstract

Objectives: To determine the frequency of familial focal and segmental dystonias in a large patient cohort with primary dystonia from north-western Germany.

Materials and methods: In this study, 130 patients with focal or segmental dystonia were examined and a family history was obtained. Whenever possible, affected relatives were examined (a total of 789 first-degree relatives). Data on disease duration, age at disease onset and age of the patients were investigated by Student's t-test and a segregation analysis was performed by Weinberg's proband method.

Results: Age at onset of disease was significantly later in the blepharospasm group. Only in the writer's cramp group were women outnumbered by men. A positive family history was found in 15 of the 130 index patients (11.5%). None of 102 index patients tested carried the GAG deletion in the DYT1 gene.

Conclusions: In accordance with previous series our study provides evidence that primary focal dystonia may have a genetic etiology, most probably caused by an autosomal dominant trait with reduced penetrance.

MeSH terms

  • Adult
  • Age of Onset
  • Aged
  • Aged, 80 and over
  • Carrier Proteins / genetics*
  • Cohort Studies
  • Dystonic Disorders / epidemiology
  • Dystonic Disorders / genetics*
  • Dystonic Disorders / pathology*
  • Female
  • Gene Deletion
  • Genetic Predisposition to Disease
  • Germany / epidemiology
  • Humans
  • Incidence
  • Male
  • Middle Aged
  • Molecular Chaperones*
  • Pedigree
  • Sex Factors

Substances

  • Carrier Proteins
  • Molecular Chaperones
  • TOR1A protein, human