Unusual and severe disease course in a child with ataxia-telangiectasia

Pediatr Allergy Immunol. 2003 Aug;14(4):330-3. doi: 10.1034/j.1399-3038.2003.00037.x.

Abstract

Ataxia-telangiectasia (AT) is an autosomal recessive syndrome of combined immunodeficiency. Hallmarks of the disease comprise progressive cerebellar ataxia, oculocutaneous telangiectasia, cancer susceptibility and variable humoral and cellular immunodeficiency. We describe a patient with AT presenting with autoimmune haemolytic anaemia, neutropenia, hepatosplenomegaly, lymphadenopathy and hyper-IgM at the age of 6 months. At the age of 26 months she developed persistent fever, progressive lymphadenopathy and pulmonary nodular infiltrates, which were responsive to steroid therapy.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Abnormalities, Multiple / blood
  • Abnormalities, Multiple / diagnosis
  • Anemia, Hemolytic, Autoimmune / blood
  • Anemia, Hemolytic, Autoimmune / diagnosis
  • Ataxia Telangiectasia / blood
  • Ataxia Telangiectasia / diagnosis*
  • Biomarkers / blood
  • Diagnosis, Differential
  • Female
  • Hepatomegaly / blood
  • Hepatomegaly / diagnosis
  • Humans
  • Immunoglobulin A / blood
  • Immunoglobulin D / blood
  • Immunoglobulin E / blood
  • Immunoglobulin G / blood
  • Immunoglobulin M / blood
  • Infant
  • Lymphatic Diseases / blood
  • Lymphatic Diseases / diagnosis
  • Neutropenia / blood
  • Neutropenia / diagnosis
  • Severity of Illness Index
  • Splenomegaly / blood
  • Splenomegaly / diagnosis
  • T-Lymphocytopenia, Idiopathic CD4-Positive / blood
  • T-Lymphocytopenia, Idiopathic CD4-Positive / diagnosis

Substances

  • Biomarkers
  • Immunoglobulin A
  • Immunoglobulin D
  • Immunoglobulin G
  • Immunoglobulin M
  • Immunoglobulin E