Polymerase chain reaction analysis of fragile X mutations

Hum Genet. 1992 Sep-Oct;90(1-2):55-61. doi: 10.1007/BF00210744.

Abstract

The mutation that underlies the fragile X syndrome is presumed to be a large expansion in the number of CGG repeats within the gene FMR-1. The unusually GC-rich composition of the expanded region has impeded attempts to amplify it by the polymerase chain reaction (PCR). We have developed a PCR protocol that successfully amplifies the (CGG)n region in normal, carrier and affected individuals. The PCR analysis of several large fragile X families is presented. The PCR results agree with those obtained by direct genomic Southern blot analyses. These favorable comparisons suggest that the PCR assay may be suitable for rapid testing for fragile X mutations and premutations and genetic screening of at-risk individuals.

Publication types

  • Comparative Study
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Base Sequence
  • Blotting, Southern
  • Female
  • Fragile X Mental Retardation Protein
  • Fragile X Syndrome / genetics*
  • Humans
  • Male
  • Molecular Sequence Data
  • Mutation / genetics
  • Nerve Tissue Proteins / genetics*
  • Oligonucleotide Probes / genetics
  • Pedigree
  • Polymerase Chain Reaction*
  • RNA-Binding Proteins*
  • Repetitive Sequences, Nucleic Acid / genetics*
  • X Chromosome*

Substances

  • FMR1 protein, human
  • Nerve Tissue Proteins
  • Oligonucleotide Probes
  • RNA-Binding Proteins
  • Fragile X Mental Retardation Protein