A case of congenital pulmonary vein stenosis in an adult

Respiration. 2004 Jan-Feb;71(1):92-4. doi: 10.1159/000075657.

Abstract

A 35-year-old Japanese woman, complaining of dyspnea after her first delivery, was diagnosed as having primary pulmonary hypertension. Continuous intravenous prostacyclin resulted in an improvement in her cardiac function, 6-min walk and New York Heart Association class, before she died of pulmonary hypertension crisis during further evaluation for pulmonary transplantation. Since the autopsy findings revealed that all 4 pulmonary veins were extremely stenotic due to hypoplasia, she was diagnosed as having had congenital pulmonary vein hypoplasia with stenosis.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Autopsy
  • Combined Modality Therapy
  • Disease Progression
  • Fatal Outcome
  • Female
  • Humans
  • Hypertension, Pulmonary / diagnosis*
  • Hypertension, Pulmonary / etiology
  • Hypertension, Pulmonary / therapy
  • Immunohistochemistry
  • Pulmonary Veno-Occlusive Disease / complications
  • Pulmonary Veno-Occlusive Disease / congenital*
  • Pulmonary Veno-Occlusive Disease / pathology*
  • Rare Diseases
  • Risk Assessment
  • Severity of Illness Index