Genetic engineering of cytolytic T lymphocytes for adoptive T-cell therapy of neuroblastoma

J Gene Med. 2004 Jun;6(6):704-11. doi: 10.1002/jgm.489.

Abstract

Background: Disease relapse is the leading cause of mortality for children diagnosed with disseminated neuroblastoma. The adoptive transfer of tumor-specific T cells is an attractive approach to target minimal residual disease following conventional therapies. We describe here the genetic engineering of human cytotoxic T lymphocytes (CTL) to express a chimeric immunoreceptor for re-directed HLA-independent recognition of neuroblastoma.

Methods: The CE7R chimeric immunoreceptor was constructed by PCR splice overlap extension and is composed of a single-chain antibody extracellular domain (scFv) derived from the L1-CAM-specific murine CE7 hybridoma fused to human IgG1 hinge-Fc, the transmembrane portion of human CD4, and the cytoplasmic tail of huCD3-zeta chain (scFvFc:zeta). Primary human T cells were genetically modified by naked DNA electrotransfer of plasmid expression vector CE7R-pMG then analyzed by Western blotting, flow cytometry for CE7R expression and cell surface trafficking, 4-h chromium release assay for re-directed neuroblastoma lysis, and ELISA for tumor-specific activation of cytokine production.

Results: CE7R is expressed as an intact chimeric protein that trafficks to the cell surface as a type I transmembrane protein. Primary human CE7R-expressing CD8(+) CTL clones specifically recognize human neuroblastoma tumor cells and are activated for tumor cell lysis and T(c)1 cytokine production.

Conclusions: These data demonstrate the utility of CE7R for re-directing the effector function of CTL to neuroblastoma and have provided the rationale to initiate a FDA-authorized (BB-IND#9149) pilot clinical trial to establish the feasibility and safety of adoptive transfer of autologous CE7R(+)CD8(+) CTL clones to children with recurrent/refractory neuroblastoma.

Publication types

  • Research Support, Non-U.S. Gov't
  • Research Support, U.S. Gov't, P.H.S.

MeSH terms

  • CD3 Complex / genetics
  • CD4 Antigens / genetics
  • CD8-Positive T-Lymphocytes / metabolism
  • Cell Membrane / genetics
  • Cell Membrane / metabolism
  • Cytokines / metabolism
  • Genetic Engineering / methods*
  • Humans
  • Hybridomas / immunology
  • Immunoglobulin G / genetics
  • Immunoglobulin Variable Region / genetics
  • Immunoglobulin Variable Region / immunology
  • Immunotherapy, Adoptive / methods*
  • Neuroblastoma / therapy*
  • Protein Transport
  • Recombinant Proteins / genetics
  • Recombinant Proteins / immunology
  • T-Lymphocytes / immunology
  • T-Lymphocytes / physiology
  • T-Lymphocytes, Cytotoxic / physiology*
  • Tumor Cells, Cultured

Substances

  • CD3 Complex
  • CD4 Antigens
  • Cd3e protein, mouse
  • Cytokines
  • Immunoglobulin G
  • Immunoglobulin Variable Region
  • Recombinant Proteins