[Mutation analysis of keratin 9 gene in a pedigree with epidermolytic palmoplantar keratoderma]

Zhonghua Yi Xue Yi Chuan Xue Za Zhi. 2004 Dec;21(6):570-3.
[Article in Chinese]

Abstract

Objective: To identify mutations of keratin 9 (KRT9) gene in a big Chinese family with epidermolytic palmoplantar keratoderma(EPPK) combined with knuckle-pad-like lesions and nail lesions.

Methods: Genomic DNA from peripheral blood of all available members in this family and 50 unrelated healthy individuals was used for amplification of the whole coding sequence and the intron-exon boundaries of KRT9 gene by PCR; The mutation was detected by direct sequence analysis and identified by restriction endonuclease Dde I.

Results: A mutation of AAT>AGT at codon 160 (N160S) was found in all patients but not in unaffected family members and 50 controls.

Conclusion: The mutation of AAT>AGT at codon 160 (N160S) is the disease-causing mutation in this Chinese pedigree with EPPK.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Asian People
  • Codon
  • DNA / genetics
  • DNA Mutational Analysis
  • Exons / genetics
  • Female
  • Genetic Predisposition to Disease*
  • Humans
  • Keratins / genetics*
  • Keratoderma, Palmoplantar / genetics*
  • Male
  • Pedigree
  • Point Mutation*
  • Polymerase Chain Reaction

Substances

  • Codon
  • Keratins
  • DNA