Split notochord syndrome variant: prenatal findings and neonatal management

Prenat Diagn. 2005 Jan;25(1):23-7. doi: 10.1002/pd.1076.

Abstract

Spilt notochord syndrome is an extremely rare form of spinal dysraphism characterized by a complete cleft of the spine and a persistent communication between endoderm and ectoderm. A variant of split notochord syndrome was diagnosed in a 25-week-old fetus showing a prolapsed congenital colostomy and a spinal cystic lesion. The final diagnosis included protruding colon segment, imperforate anus with a rectourethral fistula and lipomyelomeningocele. The ultrasound features of the condition and the post-natal management are discussed. The neonate was successfully treated with a posterior sagittal anorectoplasty, while the lipomyelomeningocele was resected at a later stage.

Publication types

  • Case Reports
  • Review

MeSH terms

  • Abnormalities, Multiple* / surgery*
  • Adult
  • Colon / abnormalities
  • Female
  • Humans
  • Infant, Newborn
  • Intestinal Fistula / congenital
  • Intestinal Fistula / surgery
  • Male
  • Meningomyelocele / pathology
  • Meningomyelocele / surgery
  • Notochord / abnormalities*
  • Pregnancy
  • Spinal Dysraphism* / complications
  • Spinal Dysraphism* / pathology
  • Spinal Dysraphism* / surgery
  • Syndrome
  • Treatment Outcome
  • Ultrasonography, Prenatal*