[A frame shift mutation, Arg346fs mutation, is identified in cardiac myosin-binding protein C gene in a Chinese family with hypertrophic cardiomyopathy]

Zhonghua Yi Xue Za Zhi. 2005 Apr 13;85(14):963-6.
[Article in Chinese]

Abstract

Objective: To explore the disease-causing gene mutation in Chinese with hypertrophic cardiomyopathy (HCM).

Methods: The peripheral venous blood samples were collected from 5 HCM families without consanguinity, including 5 probands, 2 males and 3 females, 28 sporadic HCM patients, 18 males and 10 females, and 80 healthy controls. The exons in the functional regions of cardiac myosin-binding protein C (MYBPC3) were amplified with PCR and the amplified products were sequenced.

Results: A frame shift mutation-Arg346fs mutation in exon 13, the first mutation identified in Chinese-was discovered in one family with HCM. However, the members of the same HCM family with the Arg346fs mutation showed differences in phenotype and prognosis.

Conclusion: Cardiac myosin-binding protein C (MYBPC3) may be one of the main disease-causing genes. The heterogeneity of phenotype suggests that multiple factors may be involved in the pathogenesis.

Publication types

  • English Abstract
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Adult
  • Base Sequence
  • Cardiomyopathy, Hypertrophic, Familial / genetics*
  • Carrier Proteins / genetics*
  • Child
  • China / ethnology
  • DNA Mutational Analysis
  • Female
  • Frameshift Mutation*
  • Genotype
  • Humans
  • Male
  • Middle Aged
  • Molecular Sequence Data
  • Pedigree

Substances

  • Carrier Proteins
  • myosin-binding protein C