Targeted disruption of hepatic frataxin expression causes impaired mitochondrial function, decreased life span and tumor growth in mice

Hum Mol Genet. 2005 Dec 15;14(24):3857-64. doi: 10.1093/hmg/ddi410. Epub 2005 Nov 8.

Abstract

We have disrupted expression of the mitochondrial Friedreich ataxia protein frataxin specifically in murine hepatocytes to generate mice with impaired mitochondrial function and decreased oxidative phosphorylation. These animals have a reduced life span and develop multiple hepatic tumors. Livers also show increased oxidative stress, impaired respiration and reduced ATP levels paralleled by reduced activity of iron-sulfur cluster (Fe/S) containing proteins (ISP), which all leads to increased hepatocyte turnover by promoting both apoptosis and proliferation. Accordingly, phosphorylation of the stress-inducible p38 MAP kinase was found to be specifically impaired following disruption of frataxin. Taken together, these findings indicate that frataxin may act as a mitochondrial tumor suppressor protein in mammals.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Animals
  • Apoptosis / genetics
  • Cell Proliferation
  • Frataxin
  • Hepatocytes / metabolism
  • Hepatocytes / pathology
  • Iron-Binding Proteins / genetics*
  • Iron-Binding Proteins / metabolism
  • Iron-Sulfur Proteins / metabolism
  • Liver / pathology
  • Liver / physiology*
  • Liver Neoplasms / genetics*
  • Liver Neoplasms / pathology
  • Longevity / genetics*
  • Mice
  • Mice, Inbred C57BL
  • Mice, Knockout
  • Mitochondria / genetics
  • Mitochondria / metabolism*
  • Oxidative Stress
  • Phosphorylation
  • Reactive Oxygen Species / metabolism
  • p38 Mitogen-Activated Protein Kinases / metabolism

Substances

  • Iron-Binding Proteins
  • Iron-Sulfur Proteins
  • Reactive Oxygen Species
  • p38 Mitogen-Activated Protein Kinases