A genome-wide Drosophila RNAi screen identifies DYRK-family kinases as regulators of NFAT

Nature. 2006 Jun 1;441(7093):646-50. doi: 10.1038/nature04631. Epub 2006 Mar 1.

Abstract

Precise regulation of the NFAT (nuclear factor of activated T cells) family of transcription factors (NFAT1-4) is essential for vertebrate development and function. In resting cells, NFAT proteins are heavily phosphorylated and reside in the cytoplasm; in cells exposed to stimuli that raise intracellular free Ca2+ levels, they are dephosphorylated by the calmodulin-dependent phosphatase calcineurin and translocate to the nucleus. NFAT dephosphorylation by calcineurin is countered by distinct NFAT kinases, among them casein kinase 1 (CK1) and glycogen synthase kinase 3 (GSK3). Here we have used a genome-wide RNA interference (RNAi) screen in Drosophila to identify additional regulators of the signalling pathway leading from Ca2+-calcineurin to NFAT. This screen was successful because the pathways regulating NFAT subcellular localization (Ca2+ influx, Ca2+-calmodulin-calcineurin signalling and NFAT kinases) are conserved across species, even though Ca2+-regulated NFAT proteins are not themselves represented in invertebrates. Using the screen, we have identified DYRKs (dual-specificity tyrosine-phosphorylation regulated kinases) as novel regulators of NFAT. DYRK1A and DYRK2 counter calcineurin-mediated dephosphorylation of NFAT1 by directly phosphorylating the conserved serine-proline repeat 3 (SP-3) motif of the NFAT regulatory domain, thus priming further phosphorylation of the SP-2 and serine-rich region 1 (SRR-1) motifs by GSK3 and CK1, respectively. Thus, genetic screening in Drosophila can be successfully applied to cross evolutionary boundaries and identify new regulators of a transcription factor that is expressed only in vertebrates.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Animals
  • Casein Kinase I / metabolism
  • Drosophila / enzymology*
  • Drosophila / genetics*
  • Drosophila / metabolism
  • Dyrk Kinases
  • Genome, Insect / genetics*
  • Genomics
  • Glycogen Synthase Kinase 3 / metabolism
  • Interleukin-2 / genetics
  • NFATC Transcription Factors / chemistry
  • NFATC Transcription Factors / metabolism*
  • Phosphorylation
  • Protein Serine-Threonine Kinases / classification*
  • Protein Serine-Threonine Kinases / deficiency
  • Protein Serine-Threonine Kinases / genetics
  • Protein Serine-Threonine Kinases / metabolism*
  • Protein Structure, Tertiary
  • Protein-Tyrosine Kinases / classification*
  • Protein-Tyrosine Kinases / deficiency
  • Protein-Tyrosine Kinases / genetics
  • Protein-Tyrosine Kinases / metabolism*
  • RNA Interference*
  • Transcription, Genetic / genetics

Substances

  • Interleukin-2
  • NFATC Transcription Factors
  • Protein-Tyrosine Kinases
  • Casein Kinase I
  • Protein Serine-Threonine Kinases
  • Glycogen Synthase Kinase 3