[Alpha-galactosidase A gene mutation in a Chinese family with Fabry disease mimicking clinical features of hypertrophic cardiomyopathy]

Zhonghua Xin Xue Guan Bing Za Zhi. 2006 Feb;34(2):143-7.
[Article in Chinese]

Abstract

Objective: To screen gene mutation in alpha-galactosidase A (alpha-Gal A) in a nonconsanguineous Chinese family with Fabry disease (FD) with clinical manifestations similar to hypertrophic cardiomyopathy (HCM).

Methods: Mutation analysis was performed by using purified PCR products to direct sequence analysis on an ABI-377XL automated DNA sequencer. DNA analysis of alpha-Gal A gene and physical and clinical examinations were performed in a female proband and in her relatives (15 subjects in total).

Results: Three hemizygotes and 6 heterozygotes were diagnosed for FD by the alpha-Gal A gene analysis with a missense mutation in exon 5 of the alpha-Gal A sequence, leading to a TGG32TGA substitution, which may induce the absent of tryptophan's translation (corresponded to TGG) by the terminator codon TGA. Six patients in the family were revealed as HCM by echocardiography.

Conclusions: Present results show that it is important to differentiate FD from other causes of hypertrophy in patients with cardiac hypertrophy. Screening for alpha-Gal A gene mutations in patients with FD and in their relatives could help to identify all suspected cases within the families.

Publication types

  • English Abstract

MeSH terms

  • Adolescent
  • Adult
  • Cardiomyopathy, Hypertrophic / diagnosis*
  • Child
  • DNA Mutational Analysis
  • Fabry Disease / diagnosis
  • Fabry Disease / genetics*
  • Female
  • Humans
  • Male
  • Middle Aged
  • Mutation
  • Pedigree
  • alpha-Galactosidase / genetics*

Substances

  • alpha-Galactosidase