A newly recognized, likely autosomal recessive syndrome comprising agammaglobulinemia, microcephaly, craniosynostosis, severe dermatitis, and other features

Am J Med Genet A. 2006 Jun 1;140(11):1131-5. doi: 10.1002/ajmg.a.31275.

Abstract

We present a novel, likely autosomal recessive, multi-system disorder seen in three siblings, two males and one female, born to nonconsanguineous parents. The disease manifests as agammaglobulinemia with marked microcephaly, significant developmental delay, craniosynostosis, a severe dermatitis, cleft palate, narrowing of the choanae, and blepharophimosis. The constellation of clinical signs seen in this family likely represents a new and recognizable form of agammaglobulinemia due to a defect in early B-cell maturation.

Publication types

  • Case Reports

MeSH terms

  • Abnormalities, Multiple / genetics
  • Abnormalities, Multiple / pathology*
  • Agammaglobulinemia / pathology*
  • Child, Preschool
  • Craniosynostoses / pathology*
  • Dermatitis / pathology*
  • Family Health
  • Fatal Outcome
  • Female
  • Fetal Death
  • Fingers / abnormalities
  • Genes, Recessive / genetics*
  • Gestational Age
  • Humans
  • Infant
  • Male
  • Microcephaly / pathology*
  • Syndrome
  • Toes / abnormalities