Natural history of human T-lymphotropic virus 1-associated myelopathy: a 14-year follow-up study

Arch Neurol. 2006 Nov;63(11):1560-6. doi: 10.1001/archneur.63.11.1560.

Abstract

Background: The progression of neurological disability in human T-lymphotropic virus 1 (HTLV-1)-associated myelopathy/tropical spastic paraparesis (HAM/TSP) remains undefined.

Objectives: To determine the time course of disability scores and to identify predictors of outcome among patients with HAM/TSP.

Design: Clinical 14-year follow-up study.

Setting: University hospital. Patients One hundred twenty-three patients with HAM/TSP.

Main outcome measures: We determined time from onset to the following 4 Kurtzke Disability Status Scale (DSS) end points: scores of 6 (unilateral aid required), 6.5 (bilateral aid required), 8 (wheelchair confinement), and 10 (death related to the disease). Times to reach selected DSS scores were estimated using the Kaplan-Meier method. Univariate and multivariate analyses identified variables related to the rate of progression to DSS 8. The HTLV-1 proviral loads were also assessed.

Results: The disability of the cohort progressed throughout the follow-up period. The median times from onset to DSS 6, 6.5, and 8 were 6, 13, and 21 years, respectively. The median time from DSS 6 to DSS 8 was 8 years; DSS 10 was reached by one fourth of the patients within 20 years. Age at onset of 50 years or older and high HTLV-1 proviral load were associated with a shorter time to DSS 8 (P = .01 and P = .02, respectively). A shorter time to DSS 6 significantly adversely affected the time to progression from DSS 6 to DSS 8.

Conclusions: Human T-lymphotropic virus 1-associated myelopathy/tropical spastic paraparesis is a rapidly disabling disease. Monitoring for HTLV-1 proviral load is recommended in future therapeutic trials.

Publication types

  • Comparative Study

MeSH terms

  • Age of Onset
  • Aged
  • Aged, 80 and over
  • Disability Evaluation
  • Disease Progression
  • Female
  • Follow-Up Studies
  • Human T-lymphotropic virus 1*
  • Humans
  • Male
  • Multivariate Analysis
  • Paraparesis, Tropical Spastic / diagnosis
  • Paraparesis, Tropical Spastic / epidemiology*
  • Paraparesis, Tropical Spastic / virology*
  • Predictive Value of Tests
  • Retrospective Studies
  • Risk
  • Severity of Illness Index
  • Spinal Cord Diseases / diagnosis
  • Spinal Cord Diseases / epidemiology*
  • Spinal Cord Diseases / virology*
  • Time Factors