Correction of humoral derangements from mutant superoxide dismutase 1 spinal cord

Ann Neurol. 2006 Dec;60(6):716-28. doi: 10.1002/ana.21034.

Abstract

Objective: We sought to define molecular and cellular participants that mediate motor neuron injury in amyotrophic lateral sclerosis using a coculture system.

Methods: We cocultured embryonic stem cell-derived motor neurons with organotypic slice cultures from wild-type or SOD1G93A (MT) mice. We examined axon lengths and cell survival of embryonic stem cell-derived motor neurons. We defined and quantified the humoral factors that differed between wild-type and MT organotypic cultures, and then corrected these differences in cell culture.

Results: MT spinal cord organotypic slices were selectively toxic to motor neurons as defined by axonal lengths and cell survival. MT spinal cord organotypic slices secreted higher levels of nitric oxide, interleukin (IL)-1beta, IL-6, and IL-12p70 and lower levels of vascular endothelial growth factor. The toxicity of MT spinal cord organotypic cultures was reduced and axonal lengths were restored to near normal by coculturing in the presence of reactive oxygen species scavenger, vascular endothelial growth factor, and neutralizing antibodies to IL-1beta, IL-6, and IL-12.

Interpretation: MT spinal cord organotypic cultures overexpress certain factors and underexpress others, creating a nonpermissive environment for cocultured motor neurons. Correction of these abnormalities as a group, but not individually, restores axonal length to near normal. Such a "cocktail" approach to the treatment of amyotrophic lateral sclerosis should be investigated further.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Amyotrophic Lateral Sclerosis / genetics
  • Amyotrophic Lateral Sclerosis / metabolism
  • Amyotrophic Lateral Sclerosis / therapy
  • Animals
  • Antibodies / pharmacology*
  • Antibodies / therapeutic use
  • Cell Line, Transformed
  • Cell Survival / drug effects
  • Cell Survival / physiology
  • Coculture Techniques
  • Culture Media, Conditioned / chemistry
  • Culture Media, Conditioned / toxicity
  • Disease Models, Animal
  • Female
  • Free Radical Scavengers / pharmacology*
  • Free Radical Scavengers / therapeutic use
  • Humans
  • Interleukins / antagonists & inhibitors*
  • Interleukins / metabolism
  • Interleukins / toxicity
  • Male
  • Mice
  • Mice, Transgenic
  • Motor Neurons / drug effects*
  • Motor Neurons / immunology
  • Motor Neurons / metabolism
  • Nerve Regeneration / drug effects
  • Nerve Regeneration / physiology
  • Nitric Oxide / antagonists & inhibitors*
  • Nitric Oxide / metabolism
  • Nitric Oxide / toxicity
  • Organ Culture Techniques
  • Spinal Cord / drug effects
  • Spinal Cord / enzymology
  • Spinal Cord / physiopathology
  • Superoxide Dismutase / genetics
  • Superoxide Dismutase / metabolism
  • Treatment Outcome
  • Vascular Endothelial Growth Factor A / pharmacology
  • Vascular Endothelial Growth Factor A / therapeutic use*

Substances

  • Antibodies
  • Culture Media, Conditioned
  • Free Radical Scavengers
  • Interleukins
  • Vascular Endothelial Growth Factor A
  • Nitric Oxide
  • SOD1 G93A protein
  • Superoxide Dismutase