Surgery for cystic lymphangioma in Gorlin-Goltz syndrome

Langenbecks Arch Surg. 2007 Mar;392(2):203-7. doi: 10.1007/s00423-006-0126-5. Epub 2007 Jan 13.

Abstract

Introduction: We present a case of three major lymphomesenteric cysts in a female patient with known basal cell nevus syndrome (BCNS or Gorlin-Goltz syndrome).

Discussion: Although those cysts have been reported to appear in this syndrome, the exact prevalence is not known. In this case, the patient suffered from severe and recurrent abdominal pain due to bowel obstruction.

Conclusion: By causing severe symptoms, cystic lymphangiomas are an important complication of the BCNS despite of their seldom occurrence. Surgeons confronted with intraabdominal masses in a patient with BCNS should always be aware of this manifestation of the disorder and plan interdisciplinary operations.

Publication types

  • Case Reports

MeSH terms

  • Abdominal Pain / etiology
  • Adult
  • Basal Cell Nevus Syndrome / complications*
  • Endothelium / pathology
  • Female
  • Humans
  • Lymphangioma, Cystic / diagnostic imaging
  • Lymphangioma, Cystic / etiology*
  • Lymphangioma, Cystic / pathology
  • Lymphangioma, Cystic / surgery*
  • Recurrence
  • Tomography, X-Ray Computed