Phenotypic variability of a distinct deletion in McLeod syndrome

Mov Disord. 2007 Jul 15;22(9):1358-61. doi: 10.1002/mds.21536.

Abstract

The X-linked McLeod neuroacanthocytosis syndrome strongly resembles Huntington's disease and has been reported in various countries world-wide. Herein, we report two Chilean brothers with predominant psychiatric features at disease onset including schizophrenia-like psychosis and obsessive compulsive disorder. Molecular genetic analysis revealed a small deletion in the XK gene (938-942delCTCTA), which has been already described in a North American patient of Anglo-Saxon descent and a Japanese family, presenting with seizures, muscle atrophy or chorea yet absence of psychiatric features. These findings argue against a founder effect and indicate a profound phenotypic variability associated with the 938-942delCTCTA deletion. Our report supports the inclusion of McLeod syndrome in the differential diagnosis of Huntington's disease as well as acute psychosis in male subjects.

Publication types

  • Case Reports

MeSH terms

  • Amino Acid Transport Systems, Neutral / genetics*
  • Chorea / complications
  • Chorea / genetics*
  • Chorea / pathology
  • DNA Mutational Analysis
  • Genetic Diseases, X-Linked / complications
  • Genetic Diseases, X-Linked / genetics*
  • Genetic Diseases, X-Linked / pathology
  • Humans
  • Magnetic Resonance Imaging / methods
  • Male
  • Middle Aged
  • Phenotype*
  • Sequence Deletion*
  • Siblings*
  • Tomography, X-Ray Computed / methods

Substances

  • Amino Acid Transport Systems, Neutral
  • XK protein, human