Cytogenetic investigation of a child with a mosaic isochromosome 18q and ring 18q

Eur J Med Genet. 2007 Sep-Oct;50(5):379-85. doi: 10.1016/j.ejmg.2007.06.001. Epub 2007 Jul 17.

Abstract

We report on a baby girl from non-consanguineous Palestinian parents with intrauterine growth retardation, low birth weight, and developmental delay. She had a short stature, microcephaly, a prominent metopic suture, a glabellar haemangioma, exophthalmos, hypertelorism, upslanting palpebral fissures, horizontal nystagmus, flat nose, cleft lip and palate, a short neck, widely spaced nipples, umbilical hernia, flexion deformity of the wrist, ulnar deviation of fingers, and right club foot. Cortical atrophy, enlarged ventricles, a thin corpus callosum, thoracic hemivertebrae, and a ventricular septal defect were detected as well. High resolution chromosome analysis identified in 92% of cells an isochromosome 18 and in 8% of cells a ring 18. Molecular cytogenetic investigations confirmed that it was an i(18q) and a r(18q). The hypothesis to account for this anomaly and its corresponding phenotype are discussed.

Publication types

  • Case Reports

MeSH terms

  • Abnormalities, Multiple / genetics*
  • Abnormalities, Multiple / pathology
  • Chromosomes, Human, Pair 18 / genetics*
  • Craniofacial Abnormalities / genetics
  • Craniofacial Abnormalities / pathology
  • Cytogenetic Analysis
  • Developmental Disabilities / genetics
  • Developmental Disabilities / pathology
  • Female
  • Growth Disorders / genetics
  • Growth Disorders / pathology
  • Humans
  • In Situ Hybridization, Fluorescence
  • Infant
  • Isochromosomes / genetics*
  • Models, Genetic
  • Mosaicism*
  • Phenotype
  • Ring Chromosomes*
  • Sister Chromatid Exchange