Foot length before and during insulin-like growth factor-I treatment of children with laron syndrome compared to human growth hormone treatment of children with isolated growth hormone deficiency

J Pediatr Endocrinol Metab. 2007 Dec;20(12):1325-8. doi: 10.1515/jpem.2007.20.12.1325.

Abstract

Objective: To compare foot length deficits between patients with Laron syndrome (LS) (primary growth hormone [GH] insensitivity) and congenital isolated GH deficiency (IGHD) and their response to replacement therapy with insulin-like growth factor-I (IGF-I) and hGH, respectively.

Design: Data for the study were collected from the records of nine children with LS (3 M, 6 F) 7.8 +/- 4.8 years old (mean +/- SD), and nine children with IGHD (3 M, 6 F), 3.8 +/- 3.3 years old. Fifteen non-treated adult patients with LS were also included in the study.

Methods: Measurements of foot length were recorded without treatment and monitored during 9 years of treatment in the children and in the untreated adult patients. For statistical analysis the non-parametric Mann-Whitney U test was used.

Results: With almost similar basal values in growth deficit and pre-treatment growth velocities, the achievements towards norms after 9 years of treatment were greater in the patients with IGHD than in the patients with LS: foot length reached -1.4 +/- 0.8 vs. -3.3 +/- 1.0 SDS (mean +/- SD), and body height -2.2 +/- 1.0 vs. -3.9 +/- 0.5 SDS. The difference between the two groups could be due to the initiation of replacement therapy in the patients with IGHD at a younger age. Adult foot size of untreated patients with LS is small but less retarded than the height deficit.

Conclusions: Both IGF-I and hGH are potent growth stimulating hormones of linear growth and acrae as exemplified by foot growth.

Publication types

  • Clinical Trial
  • Comparative Study

MeSH terms

  • Adolescent
  • Adult
  • Age Factors
  • Body Height / drug effects
  • Child
  • Dwarfism, Pituitary / drug therapy*
  • Dwarfism, Pituitary / physiopathology
  • Female
  • Foot / growth & development*
  • Growth Hormone / therapeutic use*
  • Hormone Replacement Therapy / methods
  • Humans
  • Insulin-Like Growth Factor I / therapeutic use*
  • Laron Syndrome / drug therapy*
  • Laron Syndrome / physiopathology
  • Male
  • Time Factors
  • Treatment Outcome

Substances

  • Insulin-Like Growth Factor I
  • Growth Hormone