Novel exon 1 progranulin gene variant in Alzheimer's disease

Eur J Neurol. 2008 Oct;15(10):1111-7. doi: 10.1111/j.1468-1331.2008.02266.x. Epub 2008 Aug 26.

Abstract

Background and purpose: Progranulin (PGRN) expression is increased in activated microglia in Alzheimer's disease (AD) brain, suggesting a potential role in this pathology.

Methods: A mutation scanning of exons and flanking regions of PGRN was carried out in 120 patients with sporadic frontotemporal lobar degeneration and 145 with sporadic AD.

Results: Amongst variants not yet deposited, a novel allelic variant was identified in Exon 1 (g100169G > A). It leads to an amino acidic change (p.Gly35Arg) and was observed in a patient with late onset AD. In silico analysis predicted that this mutation is possibly damaging. A second variant (g.100165C > T), resulting in a silent mutation (pAsp33Asp), was found in a patient with semantic dementia and in another with early onset AD. Both variants were absent in 226 controls. In addition, two rare non-pathogenic variants lying very close to PGRN splice-site regions (IVS2 + 7-->G > A and IVS7 + 7-->G > A) were observed. Transcriptional analysis in peripheral blood mononuclear cells from patients demonstrated they do not affect exon splicing.

Conclusions: A novel putative PGRN mutation leading to an amino acidic substitution was identified in a patient with clinical AD.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Age of Onset
  • Aged
  • Aged, 80 and over
  • Alzheimer Disease / epidemiology
  • Alzheimer Disease / genetics*
  • Amino Acid Substitution
  • Case-Control Studies
  • DNA Mutational Analysis
  • Dementia / epidemiology
  • Dementia / genetics*
  • Exons / genetics*
  • Female
  • Humans
  • Intercellular Signaling Peptides and Proteins / genetics*
  • Intercellular Signaling Peptides and Proteins / physiology
  • Male
  • Middle Aged
  • Polymorphism, Single Nucleotide
  • Progranulins
  • RNA Splicing
  • Sequence Analysis, DNA
  • Structure-Activity Relationship
  • Transcription, Genetic

Substances

  • GRN protein, human
  • Intercellular Signaling Peptides and Proteins
  • Progranulins