Autoimmunity and Klinefelter's syndrome: when men have two X chromosomes

J Autoimmun. 2009 Aug;33(1):31-4. doi: 10.1016/j.jaut.2009.03.006. Epub 2009 May 22.

Abstract

Similar to other autoimmune diseases, systemic lupus erythematosus (SLE) predominately affects women. Recent reports demonstrate excess Klinefelter's among men with SLE and a possible under-representation of Turner's syndrome among women with SLE as well as a case report of a 46,XX boy with SLE. These data suggest that risk of SLE is related to a gene dose effect for the X chromosome. Such an effect could be mediated by abnormal inactivation of genes on the X chromosome as has been demonstrated for CD40L, or by genetic polymorphism as has been demonstrated for Xq28. On the other hand, a gene dose effect could also be mediated by a gene without an SLE-associated polymorphism in that a gene that avoids X inactivation will have a higher level of expression in persons with two X chromosomes.

Publication types

  • Review

MeSH terms

  • Aneuploidy
  • Animals
  • CD40 Ligand / genetics
  • CD40 Ligand / immunology
  • Chromosomes, Human, X*
  • Female
  • Gene Dosage / immunology
  • Genetic Predisposition to Disease
  • Humans
  • Klinefelter Syndrome / complications
  • Klinefelter Syndrome / epidemiology
  • Klinefelter Syndrome / genetics*
  • Klinefelter Syndrome / immunology*
  • Lupus Erythematosus, Systemic / complications
  • Lupus Erythematosus, Systemic / epidemiology
  • Lupus Erythematosus, Systemic / genetics*
  • Lupus Erythematosus, Systemic / immunology
  • Male
  • Polymorphism, Genetic
  • Risk Factors
  • Sex Chromosome Aberrations*
  • Sex Factors

Substances

  • CD40 Ligand