We present a rare case of primary muscular hydatidosis in the left thigh of a 20 year-old man, who presented with painless mass. Ultrasound and magnetic resonance imaging examinations revealed a multilocular intramuscular cyst in the posteromedial compartment of the left thigh mainly occupying the adductor brevis muscle. This site of localization has not been reported previously. The patient was treated successfully by preoperative and postoperative dual treatment of albendazole together with surgery. Hydatid disease should be included in the differential diagnosis of muscular masses, regardless of its location, especially in endemic areas.