TARDBP in amyotrophic lateral sclerosis: identification of a novel variant but absence of copy number variation

J Neurol Neurosurg Psychiatry. 2009 Nov;80(11):1283-5. doi: 10.1136/jnnp.2008.166512.

Abstract

Background: Mutations in the gene encoding TDP-43 have been identified in both familial and sporadic amyotrophic lateral sclerosis (ALS).

Methods: A mutation screen and copy number analysis in a motor neuron disease clinic cohort was conducted to characterise the genetic contribution of TARDBP.

Results: A novel missense mutation in a highly conserved region of TDP-43 was identified in a patient with sporadic ALS. The mutation is in close vicinity to previously identified changes. Copy number variation abnormalities were not detected.

Conclusions: The findings stress the importance of TDP-43 in the pathogenesis of sporadic ALS.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Aged
  • Amyotrophic Lateral Sclerosis / genetics*
  • Base Sequence
  • DNA Copy Number Variations
  • DNA-Binding Proteins / genetics*
  • Female
  • Humans
  • Male
  • Middle Aged
  • Molecular Sequence Data
  • Mutation, Missense*
  • Pedigree

Substances

  • DNA-Binding Proteins