Ongoing remission after intensive ALL-type chemotherapy in pediatric intestinal T-cell lymphoma

Pediatr Blood Cancer. 2010 Apr;54(4):610-2. doi: 10.1002/pbc.22330.

Abstract

A rare case of primary intestinal T-cell lymphoma (ITL) of an 8-year-old boy is reported. Medium- to large-sized tumor cells were betaF1+, CD3+, CD8+. TIA-1+, but CD4-, CD5-, CD30-, CD56-, CD20-, CD79a-, TdT-, consistent with an intraepithelial lymphocyte (IEL) origin. They showed monoclonal rearrangement of the T-cell receptor gamma-chain and no evidence of EBV infection. No clinical, histologic, laboratory, or genetic evidence of celiac disease was detected. In adults, ITL is often associated with enteropathy and has a very poor outcome. Our patient remains in first remission 30 months after finishing the acute lymphoblastic leukemia protocol COALL-07-03 high risk standard.

Publication types

  • Case Reports

MeSH terms

  • Antineoplastic Combined Chemotherapy Protocols / therapeutic use*
  • Child
  • Cyclophosphamide / administration & dosage
  • Cytarabine / administration & dosage
  • Daunorubicin / administration & dosage
  • Dexamethasone / administration & dosage
  • Doxorubicin / administration & dosage
  • Etoposide / administration & dosage
  • Humans
  • Intestinal Neoplasms / drug therapy*
  • Intestinal Neoplasms / genetics
  • Intestinal Neoplasms / pathology*
  • Lymphoma, T-Cell / drug therapy*
  • Lymphoma, T-Cell / genetics
  • Lymphoma, T-Cell / pathology*
  • Male
  • Mercaptopurine / administration & dosage
  • Methotrexate / administration & dosage
  • Methylprednisolone / administration & dosage
  • Neoplasm Staging
  • Receptors, Antigen, T-Cell, gamma-delta / genetics
  • Remission Induction
  • Thioguanine / administration & dosage
  • Vincristine / administration & dosage

Substances

  • Receptors, Antigen, T-Cell, gamma-delta
  • Cytarabine
  • Vincristine
  • Etoposide
  • Dexamethasone
  • Doxorubicin
  • Cyclophosphamide
  • Mercaptopurine
  • Thioguanine
  • Methylprednisolone
  • Methotrexate
  • Daunorubicin