Abstract
Crystallographic analysis of the catalytic domain of PHD finger protein 8 (PHF8), an N(epsilon)-methyl lysine histone demethylase associated with mental retardation and cleft lip/palate, reveals a double-stranded beta-helix fold with conserved Fe(II) and cosubstrate binding sites typical of the 2-oxoglutarate dependent oxygenases. The PHF8 active site is highly conserved with those of the FBXL10/11demethylases, which are also selective for the di-/mono-methylated lysine states, but differs from that of the JMJD2 demethylases which are selective for tri-/di-methylated states. The results rationalize the lack of activity for the clinically observed F279S PHF8 variant and they will help to identify inhibitors selective for specific N(epsilon)-methyl lysine demethylase subfamilies.
Copyright 2010. Published by Elsevier B.V.
Publication types
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Research Support, Non-U.S. Gov't
MeSH terms
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Amino Acid Sequence
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Binding Sites / genetics
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Crystallography, X-Ray
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Histone Demethylases
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Humans
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Iron / chemistry
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Iron / metabolism
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Jumonji Domain-Containing Histone Demethylases / chemistry
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Jumonji Domain-Containing Histone Demethylases / genetics
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Jumonji Domain-Containing Histone Demethylases / metabolism
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Ketoglutaric Acids / chemistry
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Ketoglutaric Acids / metabolism
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Lysine / chemistry
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Lysine / metabolism
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Models, Molecular
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Molecular Sequence Data
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Mutation
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Protein Binding
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Protein Conformation
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Protein Structure, Tertiary*
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Sequence Homology, Amino Acid
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Transcription Factors / chemistry*
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Transcription Factors / genetics
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Transcription Factors / metabolism*
Substances
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Ketoglutaric Acids
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Transcription Factors
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Iron
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Histone Demethylases
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Jumonji Domain-Containing Histone Demethylases
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PHF8 protein, human
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Lysine