Nijmegen breakage syndrome: Long-term monitoring of viral and immunological biomarkers in peripheral blood before development of malignancy

Clin Immunol. 2010 Jun;135(3):440-7. doi: 10.1016/j.clim.2010.01.008. Epub 2010 Feb 18.

Abstract

Selected viruses and immune parameters were monitored in 57 patients with Nijmegen breakage syndrome as a proposed tool for early detection of changes preceding development of malignancy. The following parameters were analysed: (1) viral infections; (2) monoclonal proteins; and (3) B-cell and T-cell receptor gene rearrangements in peripheral blood lymphocytes. Viral infections were detected in 68.4% of patients with a predominance of EBV (63.2%), followed by HBV (19.2%) and HCV (8.8%). Monoclonal gammopathy detected in 38.6% of cases correlated with the presence of EBV DNA (p=0.002) and HCV RNA (p=0.04). Clonal Ig and/or TCR gene rearrangements occurred in 73.9% of patients. The presence of at least one of the studied parameters preceded the development of malignancy in 22 patients. Systematic PCR analysis for viral infections and Ig/TCR gene rearrangements, supplemented by detection of monoclonal proteins, is advantageous in monitoring NBS patients before severe complications of the disease, including cancer, appear.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Biomarkers, Tumor / analysis*
  • Child
  • Child, Preschool
  • Female
  • Gene Rearrangement, B-Lymphocyte
  • Gene Rearrangement, T-Lymphocyte
  • Hematologic Neoplasms / epidemiology
  • Hematologic Neoplasms / etiology*
  • Humans
  • Infant
  • Male
  • Nijmegen Breakage Syndrome / blood
  • Nijmegen Breakage Syndrome / immunology*
  • Nijmegen Breakage Syndrome / virology*
  • Paraproteinemias
  • Receptors, Antigen, B-Cell / genetics
  • Receptors, Antigen, T-Cell / genetics
  • Reverse Transcriptase Polymerase Chain Reaction
  • T-Lymphocyte Subsets / immunology
  • Virus Diseases / complications
  • Virus Diseases / epidemiology*
  • Young Adult

Substances

  • Biomarkers, Tumor
  • Receptors, Antigen, B-Cell
  • Receptors, Antigen, T-Cell