Spectrum of mutations in RARS-T patients includes TET2 and ASXL1 mutations

Leuk Res. 2010 Aug;34(8):969-73. doi: 10.1016/j.leukres.2010.02.033. Epub 2010 Mar 23.

Abstract

While a majority of patients with refractory anemia with ring sideroblasts and thrombocytosis harbor JAK2V617F and rarely MPLW515L, JAK2/MPL-negative cases constitute a diagnostic problem. 23 RARS-T cases were investigated applying immunohistochemical phospho-STAT5, sequencing and SNP-A-based karyotyping. Based on the association of TET2/ASXL1 mutations with MDS/MPN we studied molecular pattern of these genes. Two patients harbored ASXL1 and another 2 TET2 mutations. Phospho-STAT5 activation was present in one mutated TET2 and ASXL1 case. JAK2V617F/MPLW515L mutations were absent in TET2/ASXL1 mutants, indicating that similar clinical phenotype can be produced by various MPN-associated mutations and that additional unifying lesions may be present in RARS-T.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Aged
  • Aged, 80 and over
  • Anemia, Refractory / genetics*
  • Anemia, Refractory / metabolism
  • Anemia, Refractory / pathology
  • Anemia, Sideroblastic / genetics*
  • Anemia, Sideroblastic / metabolism
  • Anemia, Sideroblastic / pathology
  • DNA-Binding Proteins / genetics*
  • Dioxygenases
  • Humans
  • Immunoenzyme Techniques
  • Middle Aged
  • Mutation / genetics*
  • Polymerase Chain Reaction
  • Polymorphism, Single Nucleotide / genetics
  • Proto-Oncogene Proteins / genetics*
  • Repressor Proteins / genetics*
  • Thrombocytosis / genetics*
  • Thrombocytosis / metabolism
  • Thrombocytosis / pathology

Substances

  • ASXL1 protein, human
  • DNA-Binding Proteins
  • Proto-Oncogene Proteins
  • Repressor Proteins
  • Dioxygenases
  • TET2 protein, human