Osteoclast-type giant cell tumor of minor salivary gland with mucin-rich salivary duct carcinoma: a case report of unusual histology with immunohistochemical analysis

Oral Surg Oral Med Oral Pathol Oral Radiol Endod. 2010 Jun;109(6):870-7. doi: 10.1016/j.tripleo.2009.12.021. Epub 2010 Mar 25.

Abstract

Objective: Salivary giant cell tumor (GCT) is exceedingly rare. This article presents an additional rare case of salivary GCT with salivary duct carcinoma (SDC).

Study design and results: The patient was a 40-year-old Japanese male. The peripheral region of the tumor showed SDC and partly revealed a mucin accumulation with cancer nests, which was a mucin-rich variant of SDC. In the central region of the tumor, mononuclear ovoid tumor cells contained osteoclastic-type giant cells. SDC showed immunopositivity for gross cystic disease fluid protein-15 (GCDFP-15), androgen receptor (AR), and Her-2, whereas the giant cell lesion was negative for GCDFP-15, AR, and Her-2. Mononuclear cells in salivary GCT showed immunopositivity for epithelial membrane antigen and p53.

Conclusion: The salivary GCT was thought to be neoplastic and derived from epithelial cells. The present case is the first de novo case of intraoral salivary GCT with a mucin-rich variant of SDC.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Carcinoma, Ductal / metabolism
  • Carcinoma, Ductal / pathology*
  • Carcinoma, Ductal / surgery
  • Giant Cell Tumors / metabolism
  • Giant Cell Tumors / pathology*
  • Giant Cell Tumors / surgery
  • Humans
  • Immunohistochemistry
  • Male
  • Mucins / metabolism
  • Neoplasms, Complex and Mixed / metabolism
  • Neoplasms, Complex and Mixed / pathology*
  • Neoplasms, Complex and Mixed / surgery
  • Osteoclasts / pathology
  • Rare Diseases
  • Salivary Ducts / pathology*
  • Salivary Ducts / surgery
  • Salivary Gland Neoplasms / metabolism
  • Salivary Gland Neoplasms / pathology*
  • Salivary Gland Neoplasms / surgery
  • Salivary Glands, Minor / metabolism
  • Salivary Glands, Minor / pathology
  • Salivary Glands, Minor / surgery
  • Salivary Proteins and Peptides / metabolism
  • Treatment Outcome

Substances

  • Mucins
  • Salivary Proteins and Peptides