Two congenital cases of pigmented epithelioid melanocytoma studied by fluorescent in situ hybridization for melanocytic tumors: case reports and review of these recent topics

Dermatology. 2010;221(2):97-106. doi: 10.1159/000314160. Epub 2010 Jun 18.

Abstract

The term 'pigmented epithelioid melanocytoma' (PEM) has recently been proposed as a nosological framework grouping lesions formerly known as animal-type melanomas, sporadic epithelioid blue nevi and Carney complex-associated epithelioid blue nevi. Congenital PEMs have been reported extremely rarely and their prognosis is poorly known. Four-color fluorescent in situ hybridization (FISH) for melanocytic lesions is a recent method developed to assess the malignant potential of ambiguous melanocytic lesions. Here we describe 2 cases of congenital epithelioid and strongly pigmented melanocytic lesions consistent with PEM. No BRAF gene mutation was found in the 2 cases. FISH for melanocytic lesions was also performed. The first case proved entirely negative, whereas the second one showed a positive zone with an extra copy of chromosome 6. The prognosis and management of PEM are discussed, with a review of the available data on the history, demographics, molecular alterations and histopathological aspects of this entity. PEM seems to represent a unique low-grade melanocytic tumor with a limited potential of metastasis to lymph nodes, but a favorable long-term clinical course. The published data about FISH for melanocytic tumors, and especially PEM, are reviewed. Four-color FISH may be a useful tool to assess more accurately the prognosis of these tumors.

Publication types

  • Case Reports
  • Review

MeSH terms

  • Antigens, CD / analysis
  • Antigens, Differentiation, Myelomonocytic / analysis
  • Chromosomes, Human, Pair 6 / genetics
  • Female
  • Humans
  • In Situ Hybridization, Fluorescence
  • Infant
  • Lymph Nodes / pathology
  • Male
  • Melanoma / congenital*
  • Melanoma / diagnosis
  • Melanoma / genetics
  • Melanoma / pathology*
  • Melanoma / surgery
  • Nevus, Blue / congenital*
  • Nevus, Blue / diagnosis
  • Nevus, Blue / genetics
  • Nevus, Blue / pathology*
  • Nevus, Blue / surgery
  • Pigmentation / genetics
  • Proto-Oncogene Proteins B-raf / genetics
  • Skin Neoplasms / congenital*
  • Skin Neoplasms / diagnosis
  • Skin Neoplasms / genetics
  • Skin Neoplasms / pathology*
  • Skin Neoplasms / surgery
  • Trisomy

Substances

  • Antigens, CD
  • Antigens, Differentiation, Myelomonocytic
  • CD68 antigen, human
  • BRAF protein, human
  • Proto-Oncogene Proteins B-raf