Targeting wild-type and mutant p53 with small molecule CP-31398 blocks the growth of rhabdomyosarcoma by inducing reactive oxygen species-dependent apoptosis

Cancer Res. 2010 Aug 15;70(16):6566-76. doi: 10.1158/0008-5472.CAN-10-0942. Epub 2010 Aug 3.

Abstract

Rhabdomyosarcoma (RMS) is a common soft-tissue sarcoma of childhood in need of more effective therapeutic options. The expression of p53 in RMS is heterogeneous such that some tumors are wild-type whereas others are p53 mutant. The small molecule CP-31398 modulates both the wild-type and the mutant p53 proteins. Here, we show that CP-31398 blocks the growth of RMS cells that have either wild-type or mutant p53 status. In wild-type A204 cells, CP-31398 increased the expression of p53 and its downstream transcriptional targets, p21 and mdm2; enhanced the expression of apoptosis-related proteins; and reduced proliferation biomarkers. Flow profiling of CP-31398-treated cells indicated an enhancement in sub-G(0) and G(1) populations. CP-31398 inhibited proliferation in a manner associated with co-induction of SOX9 and p21. Apoptosis induced by CP-31398 occurred with translocation of p53 to mitochondria, leading to altered mitochondrial membrane potential, cytochrome c release, and reactive oxygen species release. In vivo, CP-31398 decreased the growth of tumor xenografts composed of wild-type or mutant p53 tumor cells, increasing tumor-free host survival. Our findings indicate that the ability of CP-31398 to modulate wild-type and mutant p53 results in the inhibition of RMS growth and invasiveness.

Publication types

  • Research Support, N.I.H., Extramural

MeSH terms

  • Animals
  • Apoptosis / drug effects*
  • Apoptosis / physiology
  • Cell Growth Processes / drug effects
  • Cell Line, Tumor
  • Cyclosporine / pharmacology
  • Cytochromes c / metabolism
  • Drug Interactions
  • Female
  • G1 Phase / drug effects
  • Humans
  • Membrane Potential, Mitochondrial / drug effects
  • Mice
  • Mitochondria / drug effects
  • Mitochondria / metabolism
  • Mutation
  • Pyrimidines / antagonists & inhibitors
  • Pyrimidines / pharmacology*
  • Reactive Oxygen Species / metabolism*
  • Rhabdomyosarcoma / drug therapy*
  • Rhabdomyosarcoma / genetics
  • Rhabdomyosarcoma / metabolism
  • Rhabdomyosarcoma / pathology
  • SOX9 Transcription Factor / biosynthesis
  • Transcriptional Activation / drug effects
  • Tumor Suppressor Protein p53 / biosynthesis
  • Tumor Suppressor Protein p53 / genetics
  • Tumor Suppressor Protein p53 / metabolism*
  • Xenograft Model Antitumor Assays

Substances

  • Pyrimidines
  • Reactive Oxygen Species
  • SOX9 Transcription Factor
  • Sox9 protein, mouse
  • Tumor Suppressor Protein p53
  • Cyclosporine
  • Cytochromes c
  • CP 31398