Early T cell differentiation lessons from T-cell acute lymphoblastic leukemia

Prog Mol Biol Transl Sci. 2010:92:121-56. doi: 10.1016/S1877-1173(10)92006-1.

Abstract

T cells develop from bone marrow-derived self-renewing hematopoietic stem cells (HSC). Upon entering the thymus, these cells undergo progressive commitment and differentiation driven by the thymic stroma and the pre-T cell receptor (pre-TCR). These processes are disrupted in T-cell acute lymphoblastic leukemia (T-ALL). More than 70% of recurring chromosomal rearrangements in T-ALL activate the expression of oncogenic transcription factors, belonging mostly to three families, basic helix-loop-helix (bHLH), homeobox (HOX), and c-MYB. This prevalence is indicative of their importance in the T lineage, and their dominant mechanisms of transformation. For example, bHLH oncoproteins inhibit E2A and HEB, revealing their tumor suppressor function in the thymus. The induction of T-ALL, nonetheless, requires collaboration with constitutive NOTCH1 signaling and the pre-TCR, as well as loss-of-function mutations for CDKN2A and PTEN. Significantly, NOTCH1, the pre-TCR pathway, and E2A/HEB proteins control critical checkpoints and branchpoints in early thymocyte development whereas several oncogenic transcription factors, HOXA9, c-MYB, SCL, and LYL-1 control HSC self-renewal. Together, these genetic lesions alter key regulatory processes in the cell, favoring self-renewal and subvert the normal control of thymocyte homeostasis.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Animals
  • Cell Differentiation*
  • DNA-Binding Proteins / metabolism
  • Gene Expression Regulation
  • Hematopoietic Stem Cells / metabolism
  • Humans
  • Oncogene Proteins / metabolism
  • Precursor T-Cell Lymphoblastic Leukemia-Lymphoma / metabolism
  • Precursor T-Cell Lymphoblastic Leukemia-Lymphoma / pathology*
  • Signal Transduction*
  • T-Lymphocytes / cytology*
  • T-Lymphocytes / metabolism
  • Thymus Gland / cytology*
  • Thymus Gland / metabolism
  • Transcription Factors / metabolism

Substances

  • DNA-Binding Proteins
  • Oncogene Proteins
  • Transcription Factors