Reactive lymphoid hyperplasia in association with 22q11.2 deletion syndrome and a BRCA2 mutation

Eur J Med Genet. 2011 Jan-Feb;54(1):63-6. doi: 10.1016/j.ejmg.2010.09.004. Epub 2010 Sep 29.

Abstract

We report an adult male with 22q11.2 deletion syndrome and a germline BRCA2 mutation who developed T-cell monoclonal lymphoid proliferation involving the skin and a polyclonal proliferation of a retroperitoneal lymph node without any identifiable infectious and inflammatory causes. This is the first report of reactive lymphoid hyperplasia in the setting of co-occurrence of 22q11.2 deletion syndrome and a BRCA2 mutation. Further cases with a similar presentation should be reported and studies should be directed to identify the possible mechanisms involved.

Publication types

  • Case Reports

MeSH terms

  • Abnormalities, Multiple / genetics
  • Abnormalities, Multiple / pathology
  • BRCA2 Protein / genetics*
  • Chromosome Deletion*
  • Chromosomes, Human, Pair 22 / genetics*
  • Humans
  • Lymph Nodes / metabolism
  • Lymph Nodes / pathology
  • Male
  • Mutation*
  • Pseudolymphoma / pathology*
  • Skin / metabolism
  • Skin / pathology
  • Syndrome
  • Young Adult

Substances

  • BRCA2 Protein