Main pulmonary artery dilation in association with congenital bicuspid aortic valve in the absence of pulmonary valve abnormality

Heart. 2010 Nov;96(21):1756-61. doi: 10.1136/hrt.2010.199109.

Abstract

Background: Main pulmonary artery (MPA) dilation is reported to occur in association with pulmonary valve (PV) abnormalities and in genetic diseases of connective tissue.

Aim: To determine whether MPA dilation occurs with bicuspid aortic valve (BAV) in the absence of PV abnormality.

Methods: MPA and aortic dimensions were investigated in 194 subjects with BAV and 178 controls matched for age, sex and body surface area (BSA) using transthoracic two-dimensional echocardiography. Using control measurements, linear regression of each parameter versus age, gender, and BSA(2/3) provided expected values. For each subject with BAV, the percentage divergence from expected value ((observed--expected value)/expected value) for each dimension was analysed.

Results: MPA and aortic measurements showed normal distribution in all subjects. PV annulus and MPA were larger in BAV; 17.7% positive divergence of MPA dimension from expected was found in diastole, and 16.7% in systole. Aortic dimensions at all levels measured were larger in BAV; divergence was greater distally than proximally (10% divergence at annulus, 31% at ascending aorta). In BAV, divergence of ascending aortic dimensions from expected values increased with age (r(2)=0.142, p=0.02), but MPA divergence from expected values did not increase with age (r(2)=0.001, p=0.296).

Conclusions: MPA dilation occurs in association with BAV in the absence of PV abnormality, suggesting primary vessel wall pathology predisposing to arterial dilation. A systemic abnormality of connective tissue common to both arteries may be responsible, or the dilation may result from a common developmental exposure as both originate from the embryologic cono-truncus.

MeSH terms

  • Abnormalities, Multiple / diagnostic imaging*
  • Abnormalities, Multiple / pathology
  • Adolescent
  • Adult
  • Aortic Valve / abnormalities*
  • Aortic Valve / pathology
  • Case-Control Studies
  • Child
  • Child, Preschool
  • Dilatation, Pathologic / diagnostic imaging
  • Female
  • Humans
  • Infant
  • Infant, Newborn
  • Male
  • Pulmonary Artery / abnormalities*
  • Pulmonary Artery / diagnostic imaging
  • Pulmonary Artery / pathology
  • Pulmonary Valve / abnormalities
  • Reference Values
  • Ultrasonography
  • Young Adult