Optic pathway glioma: long-term visual outcome in children without neurofibromatosis type-1

Pediatr Blood Cancer. 2010 Dec 1;55(6):1083-8. doi: 10.1002/pbc.22748.

Abstract

Background: Little is known about the visual outcome of children affected by an optic pathway glioma (OPG).

Procedures: We evaluated the long-term visual outcome of 32 consecutive children affected by OPG without neurofibromatosis type-1 referred to the Pediatric Department of Padua University and managed according to standardized strategies.

Results: Eight children received chemotherapy, 10 radiotherapy, 7 both chemotherapy and radiotherapy, whereas 7 were untreated. At presentation, visual acuity (VA) was normal in 22 children (13 unilaterally and 9 bilaterally), and reduced in 10. At follow-up, VA had improved in 6 patients; it was stable in 8 and worse in 18. Visual field, assessed in 29 children, was normal in 9 and reduced in 20. The number of children with some grade of visual impairment increased from 7 to 10 during follow-up. Of the 17 children in whom the tumor became significantly smaller, VA improved in 6, was stable in 3, and worse in 8. Of the 6 children with improved VA, 5 received radiotherapy, and their papilla was normal or mildly pale. After a median follow-up of 6 years, 26 patients are alive with stable disease.

Conclusions: The visual prognosis of children with OPG is unsatisfactory. Older children treated with radiotherapy seem to have a better visual outcome than younger children. Severe optic pallor at diagnosis or during follow-up may be indicative of a negative prognosis.

Publication types

  • Clinical Trial
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Antineoplastic Combined Chemotherapy Protocols / therapeutic use*
  • Child
  • Child, Preschool
  • Combined Modality Therapy
  • Female
  • Humans
  • Infant
  • Male
  • Neurofibromatosis 1 / physiopathology
  • Optic Nerve Glioma / physiopathology*
  • Optic Nerve Glioma / therapy
  • Optic Nerve Neoplasms / physiopathology*
  • Optic Nerve Neoplasms / therapy
  • Radiotherapy Dosage
  • Treatment Outcome
  • Visual Acuity / physiology*
  • Visual Fields / physiology*
  • Visual Pathways / physiopathology*