A truncated retrotransposon disrupts the GRM1 coding sequence in Coton de Tulear dogs with Bandera's neonatal ataxia

J Vet Intern Med. 2011 Mar-Apr;25(2):267-72. doi: 10.1111/j.1939-1676.2010.0666.x. Epub 2011 Jan 31.

Abstract

Background: Bandera's neonatal ataxia (BNAt) is an autosomal recessive cerebellar ataxia that affects members of the Coton de Tulear dog breed.

Objective: To identify the mutation that causes BNAt.

Animals: The study involved DNA from 112 Cotons de Tulear (including 15 puppies with signs of BNAt) and 87 DNA samples from dogs of 12 other breeds.

Methods: The BNAt locus was mapped with a genome-wide association study (GWAS). The coding exons of positional candidate gene GRM1, which encodes metabotropic glutamate receptor 1, were polymerase chain reaction (PCR)-amplified and resequenced. A 3-primer PCR assay was used to genotype individual dogs for a truncated retrotransposon inserted into exon 8 of GRM1.

Results: The GWAS indicated that the BNAt locus was in a canine chromosome 1 region that contained candidate gene GRM1. Resequencing this gene from BNAt-affected puppies indicated that exon 8 was interrupted by the insertion of a 5'-truncated retrotransposon. All 15 BNAt-affected puppies were homozygous for the insert, whereas all other Cotons de Tulear were heterozygotes (n = 43) or homozygous (n = 54) for the ancestral allele. None of the 87 dogs from 12 other breeds had the insertion allele.

Conclusions and clinical importance: BNAt is caused by a retrotransposon inserted into exon 8 of GRM1. A DNA test for the GRM1 retrotransposon insert can be used for genetic counseling and to confirm the diagnosis of BNAt.

MeSH terms

  • Age of Onset
  • Animals
  • Cerebellar Ataxia / genetics
  • Cerebellar Ataxia / veterinary*
  • DNA Mutational Analysis / veterinary
  • DNA Primers / genetics
  • Dog Diseases / genetics*
  • Dogs
  • Exons
  • Female
  • Genome-Wide Association Study
  • Genotype
  • Heterozygote
  • Homozygote
  • Male
  • Mutagenesis, Insertional
  • Mutation*
  • Open Reading Frames
  • Pedigree
  • Receptors, Metabotropic Glutamate / genetics*
  • Retroelements

Substances

  • DNA Primers
  • Receptors, Metabotropic Glutamate
  • Retroelements
  • metabotropic glutamate receptor type 1