Gene therapy for primary immunodeficiencies: looking ahead, toward gene correction

J Allergy Clin Immunol. 2011 Jun;127(6):1344-50. doi: 10.1016/j.jaci.2011.02.027. Epub 2011 Mar 25.

Abstract

Allogeneic hematopoietic stem cell transplantation is the treatment of choice for severe primary immunodeficiencies (PIDs). For patients lacking an HLA-identical donor, gene therapy is an attractive therapeutic option. Approaches based on insertion of a functional gene by using viral vectors have provided proof of concept for the ability of gene therapy to cure PIDs. However, leukemic transformation as a result of insertional mutagenesis has been observed, prompting development of novel approaches based on introduction of DNA double-strand breaks into the endogenous locus to achieve gene correction, or into a safe genomic location ("safe harbor"). Homing endonucleases and zinc finger nucleases are target-specific endonucleases that induce site-specific DNA double-strand breaks, facilitating homologous recombination around their target sites to achieve gene correction or gene insertion into safe harbors. An alternative approach to achieve site-specific insertion of functional genes is based on transposons, DNA elements that spontaneously translocate from a specific chromosomal location to another. These novel tools may lead to efficient and safer strategies to achieve gene therapy for PIDs and other disorders.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't
  • Review

MeSH terms

  • DNA Transposable Elements / genetics
  • Endonucleases / genetics
  • Genetic Therapy / adverse effects
  • Genetic Therapy / methods
  • Genetic Therapy / trends*
  • Genetic Vectors
  • Humans
  • Immunologic Deficiency Syndromes / genetics
  • Immunologic Deficiency Syndromes / immunology
  • Immunologic Deficiency Syndromes / therapy*
  • Models, Genetic
  • Targeted Gene Repair / methods
  • Targeted Gene Repair / trends
  • Transposases / genetics
  • Viruses / genetics
  • Zinc Fingers / genetics

Substances

  • DNA Transposable Elements
  • Transposases
  • Endonucleases